Alice in wonderland syndrome(AIWS) refers to distortions of body image, usually in the setting of migraine with aura. A 11-year-old girl was visited to our out-patient clinic because of severe headache and dizziness. She had experienced headache since 10 months ago, but since one month ago, her head- ache was more aggravated 2 to 4 times weekly. Severe bitemporal headaches were throbbing and lasted for about 5 hours, aggravated at usual physical activities. Associate symptoms were abdominal pain, dizziness. Visual auras were frequently occurred 2 to 3 times weekly, which were fortification spectra with scotomas, blurring of vision etc. Neurologic and psychologic examination, and MRI were normal. But 2 or 3 times weekly she complained bizarre perceptual distortions: micropsia, macropsia, metamor- phopsia, distorted distance of objects, polyopsia, auditory hallucination etc. We diagnosed her as AIWS with migraine in childhood and treated with intermittent naproxen and pro- phylactic amitriptyline. She was markedly improved 2 weeks later. Korean Journal of Headache 5(2):139-142, 2004