Ophthalmoplegic migraine(OM) is a rare disorder characterized by recurrent episodes of migraine-like headaches associated with extrinsic ocular musculature palsy. The oculomotor nerve is the most common cranial nerve affected. We present a 10 year-old girl with throbbing frontal headache, eyeball pain and oculomotor nerve palsy on the right side. T1-weighted, gadolinium-enhanced MRI showed focal thickening and enhancement of the right oculomotor nerve, which were compatible with an OM. After steroid treatment, symptoms completely resolved 2 month later. Ten month later, on the recurrent state of OM, repeated MRI revealed abnormal findings of partially resolved enhancement and persistent thickening of the right oculomotor nerve.